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Large cell calcifying Sertoli cell tumor (LCCSCT) is an uncommon testicular neoplasm.This tumor constitutes one of the conditions of Carneys complex.Sudden death may occur secondary to cardiac myxoma.1 Extra-testicular growths of LCCSCT occur in 75% of the clinically malignant cases but in none of the clinically benign cases.2 We describe the features of bilateral testicular LCCSCT with left epididymal involvement in an adolescent, which has benign characteristics.If this diagnosis can be suggested preoperatively, surgical local excision may be the choice.